Pulverulent cataract with variably associated microcornea and iris coloboma in a MAF mutation family

Br J Ophthalmol. 2003 Apr;87(4):411-2. doi: 10.1136/bjo.87.4.411.

Abstract

Aims: To report the detailed clinical findings in a three generation pedigree with autosomal dominant cataract, microcornea, and coloboma resulting from mutation of the lens development gene, MAF.

Methods: Five members of a three generation pedigree with progressive cataracts underwent detailed ophthalmic examination to characterise associated ocular phenotypic features.

Results: The cataracts present in all affected individuals were cortical, and/or nuclear, pulverulent opacities. Corneal diameters of 10-10.25 mm were present in two family members. Axial lengths were in the normal range. Bilateral iris coloboma in the 6 o'clock position was present in one patient. Uveal melanoma was present in one patient, with uveal naevi in this and one other patient.

Conclusion: The bZIP transcription factor MAF is a key lens development gene that regulates the expression of the crystallins. Individuals with a mutation in MAF may have pulverulent cataract alone or cataract in association with microcornea or iris coloboma.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Age of Onset
  • Cataract / complications
  • Cataract / genetics*
  • Coloboma / complications
  • Coloboma / genetics*
  • Cornea / abnormalities*
  • DNA-Binding Proteins / genetics
  • Family Health
  • Female
  • Humans
  • Iris / abnormalities*
  • Male
  • Middle Aged
  • Mutation / genetics
  • Pedigree
  • Phenotype
  • Proto-Oncogene Proteins / genetics
  • Proto-Oncogene Proteins c-maf

Substances

  • DNA-Binding Proteins
  • MAF protein, human
  • Proto-Oncogene Proteins
  • Proto-Oncogene Proteins c-maf